Total submissions: 3
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Labcorp Genetics |
RCV001238283 | SCV001411086 | uncertain significance | Bardet-Biedl syndrome; McKusick-Kaufman syndrome | 2021-08-24 | criteria provided, single submitter | clinical testing | This sequence change replaces asparagine with serine at codon 427 of the MKKS protein (p.Asn427Ser). The asparagine residue is moderately conserved and there is a small physicochemical difference between asparagine and serine. This variant is present in population databases (rs776235071, ExAC 0.01%). This variant has not been reported in the literature in individuals affected with MKKS-related conditions. Algorithms developed to predict the effect of missense changes on protein structure and function output the following: SIFT: "Tolerated"; PolyPhen-2: "Benign"; Align-GVGD: "Class C0". The serine amino acid residue is found in multiple mammalian species, which suggests that this missense change does not adversely affect protein function. In summary, the available evidence is currently insufficient to determine the role of this variant in disease. Therefore, it has been classified as a Variant of Uncertain Significance. |
Fulgent Genetics, |
RCV005036520 | SCV005663371 | uncertain significance | McKusick-Kaufman syndrome; Bardet-Biedl syndrome 6 | 2024-01-22 | criteria provided, single submitter | clinical testing | |
Prevention |
RCV004734067 | SCV005361684 | uncertain significance | MKKS-related disorder | 2024-05-10 | no assertion criteria provided | clinical testing | The MKKS c.1280A>G variant is predicted to result in the amino acid substitution p.Asn427Ser. To our knowledge, this variant has not been reported in the literature. This variant is reported in 0.013% of alleles in individuals of African descent in gnomAD. At this time, the clinical significance of this variant is uncertain due to the absence of conclusive functional and genetic evidence. |