Total submissions: 5
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Invitae | RCV000457948 | SCV000553509 | likely benign | DICER1-related tumor predisposition | 2024-01-24 | criteria provided, single submitter | clinical testing | |
Ambry Genetics | RCV000561152 | SCV000661815 | likely benign | Hereditary cancer-predisposing syndrome | 2024-04-19 | criteria provided, single submitter | clinical testing | This alteration is classified as likely benign based on a combination of the following: seen in unaffected individuals, population frequency, intact protein function, lack of segregation with disease, co-occurrence, RNA analysis, in silico models, amino acid conservation, lack of disease association in case-control studies, and/or the mechanism of disease or impacted region is inconsistent with a known cause of pathogenicity. |
St. |
RCV000457948 | SCV001761643 | uncertain significance | DICER1-related tumor predisposition | 2021-06-17 | criteria provided, single submitter | clinical testing | The DICER1 c.4804G>A (p.Ala1602Thr) missense change has a maximum subpopulation frequency of 0.016% in gnomAD v2.1.1 (https://gnomad.broadinstitute.org/variant/14-95562453-C-T?dataset=gnomad_r2_1). Five of seven in silico tools predict a benign effect of this variant on protein function (BP4), but to our knowledge these predictions have not been confirmed by functional assays. Although this variant occurs in a gene where missense variants are more likely to be damaging (PMID: 27535533), the variant lies at a residue that has a constrained coding region score of 0 and is not predicted to be more damaging based on methods described by Havrilla et al (PMID: 30531870). This variant was identified in 1/1358 non-cancer control individuals in a study of individuals with multiple primary cancers (PMID: 29641532). To our knowledge, this variant has not been reported in individuals with DICER1 syndrome. In summary, this variant meets criteria to be classified as of uncertain significance based on the ACMG/AMP criteria: BP4. |
Sema4, |
RCV000561152 | SCV002533023 | uncertain significance | Hereditary cancer-predisposing syndrome | 2022-01-02 | criteria provided, single submitter | curation | |
Center for Genomic Medicine, |
RCV002268092 | SCV002551485 | uncertain significance | not specified | 2024-07-31 | criteria provided, single submitter | clinical testing |