Total submissions: 8
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Clin |
RCV001202699 | SCV004231824 | uncertain significance | DICER1-related tumor predisposition | 2024-01-09 | reviewed by expert panel | curation | The NM_177438.2: c.5171C>T variant in DICER1 is a missense variant predicted to cause substitution of proline by leucine at amino acid 1724 (p.Pro1724Leu). The highest population minor allele frequency in gnomAD v4.0.0 is 0.00001872 (1/53418 alleles) in European (Finnish) population, followed by 0.00001159 (1/86256 alleles) in South Asian population (PM2_Supporting, BS1, and BA1 are not met). This variant resides within the RNase IIIb mutational hotspot domain with critical functionality as defined by the ClinGen DICER1 VCEP (PM1_Supporting; PMID: 31342592). In silico tools predict no damaging impact of the variant on protein function (REVEL: 0.45; MaxEntScan and SpliceAI: no effect on splicing) (BP4). Due to conflicting evidence, this variant is classified as Uncertain Significance for DICER1-related tumor predisposition based on the ACMG/AMP criteria applied, as specified by the ClinGen DICER1 VCEP: PM1_Supporting, BP4. (Bayesian Points: 0; VCEP specifications version 1.2.0; 01/09/2024) |
Prevention |
RCV000851426 | SCV000993708 | uncertain significance | not provided | 2016-03-24 | criteria provided, single submitter | clinical testing | |
Labcorp Genetics |
RCV001202699 | SCV001373822 | uncertain significance | DICER1-related tumor predisposition | 2023-06-09 | criteria provided, single submitter | clinical testing | This variant has not been reported in the literature in individuals affected with DICER1-related conditions. This variant is not present in population databases (gnomAD no frequency). This sequence change replaces proline, which is neutral and non-polar, with leucine, which is neutral and non-polar, at codon 1724 of the DICER1 protein (p.Pro1724Leu). ClinVar contains an entry for this variant (Variation ID: 690455). In summary, the available evidence is currently insufficient to determine the role of this variant in disease. Therefore, it has been classified as a Variant of Uncertain Significance. Advanced modeling of protein sequence and biophysical properties (such as structural, functional, and spatial information, amino acid conservation, physicochemical variation, residue mobility, and thermodynamic stability) performed at Invitae indicates that this missense variant is not expected to disrupt DICER1 protein function. |
Baylor Genetics | RCV001202699 | SCV001481642 | uncertain significance | DICER1-related tumor predisposition | 2020-01-07 | criteria provided, single submitter | clinical testing | This variant was determined to be of uncertain significance according to ACMG Guidelines, 2015 [PMID:25741868]. |
Institute for Clinical Genetics, |
RCV000851426 | SCV002010932 | uncertain significance | not provided | 2021-11-03 | criteria provided, single submitter | clinical testing | |
Ambry Genetics | RCV002336748 | SCV002644984 | uncertain significance | Hereditary cancer-predisposing syndrome | 2023-08-01 | criteria provided, single submitter | clinical testing | The p.P1724L variant (also known as c.5171C>T), located in coding exon 23 of the DICER1 gene, results from a C to T substitution at nucleotide position 5171. The proline at codon 1724 is replaced by leucine, an amino acid with similar properties. This amino acid position is highly conserved in available vertebrate species. In addition, the in silico prediction for this alteration is inconclusive. Since supporting evidence is limited at this time, the clinical significance of this alteration remains unclear. |
Fulgent Genetics, |
RCV002495213 | SCV002783393 | uncertain significance | Euthyroid goiter; Rhabdomyosarcoma, embryonal, 2; Pleuropulmonary blastoma; Global developmental delay - lung cysts - overgrowth - Wilms tumor syndrome | 2022-02-08 | criteria provided, single submitter | clinical testing | |
Center for Genomic Medicine, |
RCV003321754 | SCV004026717 | uncertain significance | not specified | 2023-08-15 | criteria provided, single submitter | clinical testing |