Total submissions: 4
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
3billion | RCV001807934 | SCV002058229 | likely pathogenic | Retinitis pigmentosa 88 | 2022-01-03 | criteria provided, single submitter | clinical testing | Frameshift: predicted to result in a loss or disruption of normal protein function through nonsense-mediated decay (NMD) or protein truncation. Multiple pathogenic variants are reported downstream of the variant (PVS1_VS). It is observed at an extremely low frequency in the gnomAD v2.1.1 dataset (total allele frequency: 0.000041, PM2_M). Therefore, this variant is classified as likely pathogenic according to the recommendation of ACMG/AMP guideline. |
Labcorp Genetics |
RCV001869574 | SCV002187286 | uncertain significance | not provided | 2022-08-24 | criteria provided, single submitter | clinical testing | This premature translational stop signal has been observed in individual(s) with retinitis pigmentosa (PMID: 27029556, 31087526). This variant is present in population databases (rs770312128, gnomAD 0.02%). This sequence change creates a premature translational stop signal (p.Lys111Glnfs*27) in the RP1L1 gene. It is expected to result in an absent or disrupted protein product. However, the current clinical and genetic evidence is not sufficient to establish whether loss-of-function variants in RP1L1 cause disease. ClinVar contains an entry for this variant (Variation ID: 1333246). In summary, the available evidence is currently insufficient to determine the role of this variant in disease. Therefore, it has been classified as a Variant of Uncertain Significance. |
Dept Of Ophthalmology, |
RCV003888323 | SCV004706000 | uncertain significance | Retinal dystrophy | 2023-10-01 | criteria provided, single submitter | research | |
Clinical Genetics Laboratory, |
RCV001869574 | SCV005198077 | likely pathogenic | not provided | 2024-01-02 | criteria provided, single submitter | clinical testing |