Total submissions: 2
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Neuberg Centre For Genomic Medicine, |
RCV001823608 | SCV002073178 | uncertain significance | Emery-Dreifuss muscular dystrophy 5, autosomal dominant | criteria provided, single submitter | clinical testing | The missense variant p.L4056R in SYNE2 (NM_182914.3) has not been reported previously as a pathogenic variant nor as a benign variant, to our knowledge. The p.L4056R variant is novel (not in any individuals) in gnomAD Exomes and is novel (not in any individuals) in 1000 Genomes. There is a moderate physicochemical difference between leucine and arginine. The p.L4056R missense variant is predicted to be damaging by both SIFT and PolyPhen2. The nucleotide c.12167 in SYNE2 is predicted conserved by GERP++ and PhyloP across 100 vertebrates. For these reasons, this variant has been classified as Uncertain Significance. | |
Revvity Omics, |
RCV001823608 | SCV003818259 | uncertain significance | Emery-Dreifuss muscular dystrophy 5, autosomal dominant | 2022-04-28 | criteria provided, single submitter | clinical testing |