Total submissions: 4
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Eurofins Ntd Llc |
RCV000177963 | SCV000229928 | uncertain significance | not provided | 2015-01-22 | criteria provided, single submitter | clinical testing | |
Labcorp Genetics |
RCV001223487 | SCV001395639 | uncertain significance | Emery-Dreifuss muscular dystrophy 5, autosomal dominant | 2024-04-13 | criteria provided, single submitter | clinical testing | This sequence change replaces lysine, which is basic and polar, with glutamic acid, which is acidic and polar, at codon 1859 of the SYNE2 protein (p.Lys1859Glu). This variant is present in population databases (rs201327410, gnomAD 0.008%). This variant has not been reported in the literature in individuals affected with SYNE2-related conditions. ClinVar contains an entry for this variant (Variation ID: 197053). Algorithms developed to predict the effect of missense changes on protein structure and function output the following: SIFT: "Not Available"; PolyPhen-2: "Benign"; Align-GVGD: "Not Available". The glutamic acid amino acid residue is found in multiple mammalian species, which suggests that this missense change does not adversely affect protein function. In summary, the available evidence is currently insufficient to determine the role of this variant in disease. Therefore, it has been classified as a Variant of Uncertain Significance. |
Ambry Genetics | RCV004020119 | SCV003585697 | uncertain significance | not specified | 2021-10-14 | criteria provided, single submitter | clinical testing | The c.5575A>G (p.K1859E) alteration is located in exon 38 (coding exon 37) of the SYNE2 gene. This alteration results from a A to G substitution at nucleotide position 5575, causing the lysine (K) at amino acid position 1859 to be replaced by a glutamic acid (E). Based on insufficient or conflicting evidence, the clinical significance of this alteration remains unclear. |
Revvity Omics, |
RCV001223487 | SCV003818813 | likely benign | Emery-Dreifuss muscular dystrophy 5, autosomal dominant | 2023-05-18 | criteria provided, single submitter | clinical testing |