Total submissions: 5
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Centre for Mendelian Genomics, |
RCV000626868 | SCV000747571 | pathogenic | Cavernous hemangioma | 2017-01-01 | criteria provided, single submitter | clinical testing | |
Prevention |
RCV000721907 | SCV000853059 | pathogenic | not provided | 2016-03-21 | criteria provided, single submitter | clinical testing | |
Genomic Medicine Lab, |
RCV001007911 | SCV001167620 | pathogenic | Cerebral cavernous malformation | 2018-11-29 | criteria provided, single submitter | clinical testing | |
Labcorp Genetics |
RCV001007911 | SCV001229905 | pathogenic | Cerebral cavernous malformation | 2021-03-14 | criteria provided, single submitter | clinical testing | For these reasons, this variant has been classified as Pathogenic. Loss-of-function variants in KRIT1 are known to be pathogenic (PMID: 10508515, 11222804, 12404106, 24689081). This variant has been observed in several individuals with cerebral cavernous malformations (PMID: 10545614, 23595507, 24466005). This variant is also known as 281C>G, S94X in the literature. ClinVar contains an entry for this variant (Variation ID: 523476). This variant is not present in population databases (ExAC no frequency). This sequence change creates a premature translational stop signal (p.Ser301*) in the KRIT1 gene. It is expected to result in an absent or disrupted protein product. |
Centre for Mendelian Genomics, |
RCV001007911 | SCV001367653 | pathogenic | Cerebral cavernous malformation | 2020-03-15 | criteria provided, single submitter | clinical testing | This variant was classified as: Pathogenic. The following ACMG criteria were applied in classifying this variant: PVS1,PS4_MOD,PM2,PP4. |