Total submissions: 4
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Ludwig Lab, |
RCV001847914 | SCV000258550 | pathogenic | Isolated cleft palate | 2015-12-01 | criteria provided, single submitter | research | |
Ce |
RCV002057047 | SCV002496479 | likely pathogenic | not provided | 2022-02-01 | criteria provided, single submitter | clinical testing | |
Gene |
RCV002057047 | SCV005079735 | uncertain significance | not provided | 2024-01-06 | criteria provided, single submitter | clinical testing | Not observed at significant frequency in large population cohorts (gnomAD); In silico analysis supports a deleterious effect on splicing; This variant is associated with the following publications: (PMID: 31785789, 28714951, 35982159, 35982160, 27018475) |
Labcorp Genetics |
RCV005090025 | SCV005834145 | pathogenic | Van der Woude syndrome 2 | 2024-02-20 | criteria provided, single submitter | clinical testing | This sequence change affects codon 246 of the GRHL3 mRNA. It is a 'silent' change, meaning that it does not change the encoded amino acid sequence of the GRHL3 protein. This variant is present in population databases (no rsID available, gnomAD 0.004%). This variant has been observed in individual(s) with GRHL3-related conditions (PMID: 27018475). In at least one individual the variant was observed to be de novo. ClinVar contains an entry for this variant (Variation ID: 219243). Algorithms developed to predict the effect of sequence changes on RNA splicing suggest that this variant may create or strengthen a splice site. For these reasons, this variant has been classified as Pathogenic. |