Total submissions: 3
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Labcorp Genetics |
RCV002532334 | SCV000824369 | likely benign | Dyskeratosis congenita, autosomal dominant 2; Idiopathic Pulmonary Fibrosis | 2023-11-11 | criteria provided, single submitter | clinical testing | |
St. |
RCV001775147 | SCV002012372 | uncertain significance | Dyskeratosis congenita | 2021-08-19 | criteria provided, single submitter | clinical testing | The TERT c.702G>C (p.Leu234Phe) missense change has a maximum subpopulation frequency of 0.0063% in gnomAD v2.1.1 (https://gnomad.broadinstitute.org/variant/5-1294299-C-G). This variant occurs in a gene where missense variants are more likely to be damaging based on methods described by Lek et al. (PP2; PMID: 27535533). Six of seven in silico tools predict a benign effect of this variant on protein function (BP4), but to our knowledge these predictions have not been confirmed by functional assays. To our knowledge, this variant has not been reported in individuals with clinical features of dyskeratosis congenita. In summary, this variant meets criteria to be classified as of uncertain significance based on the ACMG/AMP criteria: PP2, BP4. |
Ambry Genetics | RCV001775147 | SCV002666597 | uncertain significance | Dyskeratosis congenita | 2022-03-16 | criteria provided, single submitter | clinical testing | The p.L234F variant (also known as c.702G>C), located in coding exon 2 of the TERT gene, results from a G to C substitution at nucleotide position 702. The leucine at codon 234 is replaced by phenylalanine, an amino acid with highly similar properties. This amino acid position is conserved. In addition, this alteration is predicted to be tolerated by in silico analysis. Since supporting evidence is limited at this time, the clinical significance of this alteration remains unclear. |