Total submissions: 2
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Gene |
RCV000414144 | SCV000491284 | pathogenic | not provided | 2016-11-24 | criteria provided, single submitter | clinical testing | The c.217delG variant in the KIF7 gene has been reported previously in the homozygous state in two related individuals with Joubert syndrome (Dafinger et al., 2011). This variant causes a frameshift starting with codon Alanine 73, changes this amino acid to a Proline residue, and creates a premature Stop codon at position 109 of the new reading frame, denoted p.Ala73ProfsX109. This variant is predicted to cause loss of normal protein function either through protein truncation or nonsense-mediated mRNA decay. The c.217delG variant was not observed in approximately 2300 individuals of European and African American ancestry in the NHLBI Exome Sequencing Project, indicating it is not a common benign variant in these populations. We interpret c.217delG as a pathogenic variant. |
OMIM | RCV000023886 | SCV000045177 | pathogenic | Joubert syndrome 12 | 2011-07-01 | no assertion criteria provided | literature only |