Total submissions: 3
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Labcorp Genetics |
RCV001698934 | SCV004343614 | uncertain significance | Congenital myasthenic syndrome 8 | 2023-08-17 | criteria provided, single submitter | clinical testing | This sequence change replaces valine, which is neutral and non-polar, with methionine, which is neutral and non-polar, at codon 1667 of the AGRN protein (p.Val1667Met). This variant is present in population databases (rs770750909, gnomAD 0.006%). This missense change has been observed in individual(s) with clinical features of AGRN-related conditions (PMID: 35670010). ClinVar contains an entry for this variant (Variation ID: 1284257). An algorithm developed to predict the effect of missense changes on protein structure and function (PolyPhen-2) suggests that this variant is likely to be disruptive. In summary, the available evidence is currently insufficient to determine the role of this variant in disease. Therefore, it has been classified as a Variant of Uncertain Significance. |
Gene |
RCV004728784 | SCV005331578 | uncertain significance | not provided | 2024-01-09 | criteria provided, single submitter | clinical testing | Reported in the published literature in a patient with congenital myasthenia who also harbors and additional missense variant in the AGRN gene (PMID: 35670010); Not observed at significant frequency in large population cohorts (gnomAD); In silico analysis supports that this missense variant does not alter protein structure/function; This variant is associated with the following publications: (PMID: 35670010) |
Department of Neurology, |
RCV001698934 | SCV001916962 | pathogenic | Congenital myasthenic syndrome 8 | 2021-09-22 | no assertion criteria provided | clinical testing |