Total submissions: 3
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Labcorp Genetics |
RCV001215390 | SCV001387130 | pathogenic | Familial hemophagocytic lymphohistiocytosis 3 | 2023-12-01 | criteria provided, single submitter | clinical testing | This sequence change creates a premature translational stop signal (p.Leu826Glnfs*20) in the UNC13D gene. It is expected to result in an absent or disrupted protein product. Loss-of-function variants in UNC13D are known to be pathogenic (PMID: 14622600). This variant is present in population databases (no rsID available, gnomAD 0.004%). This premature translational stop signal has been observed in individual(s) with familial hemophagocytic lymphohistiocytosis (PMID: 19704116, 21248318). ClinVar contains an entry for this variant (Variation ID: 944890). For these reasons, this variant has been classified as Pathogenic. |
Diagnostic Laboratory, |
RCV001529007 | SCV001741719 | pathogenic | not provided | no assertion criteria provided | clinical testing | ||
Clinical Genetics DNA and cytogenetics Diagnostics Lab, |
RCV001529007 | SCV001968315 | pathogenic | not provided | no assertion criteria provided | clinical testing |