Total submissions: 4
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Gene |
RCV000760359 | SCV000890221 | pathogenic | not provided | 2023-09-05 | criteria provided, single submitter | clinical testing | Nonsense variant predicted to result in protein truncation or nonsense mediated decay in a gene for which loss of function is a known mechanism of disease; Not observed at significant frequency in large population cohorts (gnomAD); This variant is associated with the following publications: (PMID: 30511534, 25642806) |
Labcorp Genetics |
RCV000760359 | SCV001393612 | pathogenic | not provided | 2023-12-30 | criteria provided, single submitter | clinical testing | This sequence change creates a premature translational stop signal (p.Arg271*) in the ADGRG1 gene. It is expected to result in an absent or disrupted protein product. Loss-of-function variants in ADGRG1 are known to be pathogenic (PMID: 15044805, 20929962). This variant is present in population databases (rs768441855, gnomAD 0.003%). This premature translational stop signal has been observed in individuals with bilateral frontoparietal polymicrogyria (PMID: 25642806, 30511534). It has also been observed to segregate with disease in related individuals. ClinVar contains an entry for this variant (Variation ID: 620113). For these reasons, this variant has been classified as Pathogenic. |
Fulgent Genetics, |
RCV005010758 | SCV005640243 | pathogenic | Bilateral frontoparietal polymicrogyria; Polymicrogyria, bilateral perisylvian, autosomal recessive | 2024-03-05 | criteria provided, single submitter | clinical testing | |
OMIM | RCV003328470 | SCV004035029 | pathogenic | Bilateral frontoparietal polymicrogyria | 2023-09-12 | no assertion criteria provided | literature only |