Total submissions: 5
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Mendelics | RCV000986951 | SCV001136111 | likely pathogenic | Retinitis pigmentosa 26 | 2019-05-28 | criteria provided, single submitter | clinical testing | |
Labcorp Genetics |
RCV001203143 | SCV001374293 | pathogenic | not provided | 2024-11-25 | criteria provided, single submitter | clinical testing | This sequence change replaces glycine, which is neutral and non-polar, with aspartic acid, which is acidic and polar, at codon 119 of the CERKL protein (p.Gly119Asp). This variant is present in population databases (no rsID available, gnomAD 0.006%). This missense change has been observed in individual(s) with clinical features of cone-rod dystrophy and/or clinical features of retinitis pigmentosa (PMID: 26766544, 30337596; internal data). In at least one individual the data is consistent with being in trans (on the opposite chromosome) from a pathogenic variant. ClinVar contains an entry for this variant (Variation ID: 801838). Invitae Evidence Modeling of protein sequence and biophysical properties (such as structural, functional, and spatial information, amino acid conservation, physicochemical variation, residue mobility, and thermodynamic stability) indicates that this missense variant is expected to disrupt CERKL protein function with a positive predictive value of 95%. For these reasons, this variant has been classified as Pathogenic. |
Institute of Medical Genetics and Applied Genomics, |
RCV000986951 | SCV002605266 | likely pathogenic | Retinitis pigmentosa 26 | 2022-11-21 | criteria provided, single submitter | clinical testing | |
Baylor Genetics | RCV000986951 | SCV005057396 | pathogenic | Retinitis pigmentosa 26 | 2024-02-27 | criteria provided, single submitter | clinical testing | |
Natera, |
RCV000986951 | SCV002080294 | uncertain significance | Retinitis pigmentosa 26 | 2020-11-17 | no assertion criteria provided | clinical testing |