Total submissions: 3
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Department of Human Genetics, |
RCV000007231 | SCV003935296 | likely pathogenic | Spondylocostal dysostosis 1, autosomal recessive | 2023-06-28 | criteria provided, single submitter | clinical testing | |
Invitae | RCV003555952 | SCV004298381 | pathogenic | not provided | 2023-11-25 | criteria provided, single submitter | clinical testing | This sequence change creates a premature translational stop signal (p.Ala317Argfs*17) in the DLL3 gene. It is expected to result in an absent or disrupted protein product. Loss-of-function variants in DLL3 are known to be pathogenic (PMID: 12746394). This variant is present in population databases (rs786200900, gnomAD 0.01%). This premature translational stop signal has been observed in individual(s) with spondylocostal dysostosis (PMID: 10742114). ClinVar contains an entry for this variant (Variation ID: 6829). For these reasons, this variant has been classified as Pathogenic. |
OMIM | RCV000007231 | SCV000027427 | pathogenic | Spondylocostal dysostosis 1, autosomal recessive | 2000-04-01 | no assertion criteria provided | literature only |