Total submissions: 3
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Counsyl | RCV000674831 | SCV000800232 | uncertain significance | Usher syndrome type 2A; Retinitis pigmentosa 39 | 2018-05-29 | criteria provided, single submitter | clinical testing | |
Labcorp Genetics |
RCV001230929 | SCV001403429 | pathogenic | not provided | 2023-08-28 | criteria provided, single submitter | clinical testing | ClinVar contains an entry for this variant (Variation ID: 558542). This missense change has been observed in individual(s) with Usher syndrome and/or retinitis pigmentosa (PMID: 24944099; Invitae). In at least one individual the data is consistent with being in trans (on the opposite chromosome) from a pathogenic variant. This variant is not present in population databases (gnomAD no frequency). This sequence change replaces aspartic acid, which is acidic and polar, with asparagine, which is neutral and polar, at codon 3553 of the USH2A protein (p.Asp3553Asn). Advanced modeling of protein sequence and biophysical properties (such as structural, functional, and spatial information, amino acid conservation, physicochemical variation, residue mobility, and thermodynamic stability) has been performed at Invitae for this missense variant, however the output from this modeling did not meet the statistical confidence thresholds required to predict the impact of this variant on USH2A protein function. For these reasons, this variant has been classified as Pathogenic. |
Revvity Omics, |
RCV001230929 | SCV003828076 | uncertain significance | not provided | 2019-07-23 | criteria provided, single submitter | clinical testing |