Total submissions: 6
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Laboratory for Molecular Medicine, |
RCV000219645 | SCV000271166 | likely benign | not specified | 2015-02-26 | criteria provided, single submitter | clinical testing | c.3158-7A>G in intron 15 of USH2A: This variant is not expected to have clinical significance because it has been identified in 0.3% (28/10558) of African chrom osomes by the Exome Aggregation Consortium (ExAC, http://exac.broadinstitute.or g; dbSNP rs201558076). |
Gene |
RCV000923215 | SCV000534936 | likely benign | not provided | 2020-08-31 | criteria provided, single submitter | clinical testing | |
Labcorp Genetics |
RCV000923215 | SCV001068683 | benign | not provided | 2024-01-28 | criteria provided, single submitter | clinical testing | |
Genome- |
RCV003445707 | SCV004172171 | benign | Retinitis pigmentosa 39 | 2023-04-11 | criteria provided, single submitter | clinical testing | |
Genome- |
RCV003445706 | SCV004172172 | benign | Usher syndrome type 2A | 2023-04-11 | criteria provided, single submitter | clinical testing | |
Women's Health and Genetics/Laboratory Corporation of America, |
RCV000219645 | SCV005185735 | uncertain significance | not specified | 2024-05-15 | criteria provided, single submitter | clinical testing | Variant summary: USH2A c.3158-7A>G alters a conserved nucleotide located close to a canonical splice site and therefore could affect mRNA splicing, leading to a significantly altered protein sequence. Consensus agreement among computation tools predict no significant impact on normal splicing. However, these predictions have yet to be confirmed by functional studies. The variant allele was found at a frequency of 0.00016 in 1613844 control chromosomes, predominantly at a frequency of 0.0029 within the African or African-American subpopulation in the gnomAD database, including 2 homozygotes. This frequency is not significantly higher than estimated for a pathogenic variant in USH2A causing Usher Syndrome (0.00016 vs 0.011), allowing no conclusion about variant significance. To our knowledge, no occurrence of c.3158-7A>G in individuals affected with Usher Syndrome and no experimental evidence demonstrating its impact on protein function have been reported. ClinVar contains an entry for this variant (Variation ID: 228212). Based on the evidence outlined above, the variant was classified as VUS-possibly benign. |