Total submissions: 8
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Counsyl | RCV000669591 | SCV000794360 | uncertain significance | Usher syndrome type 2A; Retinitis pigmentosa 39 | 2017-10-06 | criteria provided, single submitter | clinical testing | |
Laboratory for Molecular Medicine, |
RCV000826079 | SCV000967574 | uncertain significance | not specified | 2019-02-05 | criteria provided, single submitter | clinical testing | The p.Gln2951Glu variant in USH2A has been reported in 1 individual with retinitis pigmentosa who also had two additional variants of uncertain significance in USH2A (Carss 2017). This variant has been reported in ClinVar (Variation ID 438029), and it has also been identified in 0.01% (1/8708) of African chromosomes by gnomAD (http://gnomad.broadinstitute.org). Computational prediction tools and conservation analysis do not provide strong support for or against an impact to the protein. In summary, the clinical significance of this variant is uncertain. ACMG/AMP Criteria applied: PM2_Supporting. |
Labcorp Genetics |
RCV001857207 | SCV002119817 | uncertain significance | not provided | 2022-11-01 | criteria provided, single submitter | clinical testing | This sequence change replaces glutamine, which is neutral and polar, with glutamic acid, which is acidic and polar, at codon 2951 of the USH2A protein (p.Gln2951Glu). This variant is present in population databases (rs201394390, gnomAD 0.01%). This missense change has been observed in individual(s) with retinitis pigmentosa (PMID: 28041643). ClinVar contains an entry for this variant (Variation ID: 438029). Advanced modeling of protein sequence and biophysical properties (such as structural, functional, and spatial information, amino acid conservation, physicochemical variation, residue mobility, and thermodynamic stability) performed at Invitae indicates that this missense variant is not expected to disrupt USH2A protein function. In summary, the available evidence is currently insufficient to determine the role of this variant in disease. Therefore, it has been classified as a Variant of Uncertain Significance. |
Gene |
RCV001857207 | SCV003933167 | uncertain significance | not provided | 2023-06-02 | criteria provided, single submitter | clinical testing | Not observed at significant frequency in large population cohorts (gnomAD); In silico analysis supports that this missense variant does not alter protein structure/function; This variant is associated with the following publications: (PMID: 28041643) |
Genome- |
RCV003449427 | SCV004182762 | uncertain significance | Retinitis pigmentosa 39 | 2023-11-04 | criteria provided, single submitter | clinical testing | |
Genome- |
RCV001834623 | SCV004182763 | uncertain significance | Usher syndrome type 2A | 2023-11-04 | criteria provided, single submitter | clinical testing | |
NIHR Bioresource Rare Diseases, |
RCV000504737 | SCV000598835 | uncertain significance | Retinitis pigmentosa | 2015-01-01 | no assertion criteria provided | research | |
Natera, |
RCV001834623 | SCV002090802 | uncertain significance | Usher syndrome type 2A | 2020-09-29 | no assertion criteria provided | clinical testing |